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Phosphoenolpyruvate carboxykinase deficiency

ORPHA:2880DiseaseAutosomal recessive, Mitochondrial inheritanceInfancy, Neonatal

Ассоциированные гены (2)

PCK1
phosphoenolpyruvate carboxykinase 1
Disease-causing germline mutation(s) in
OMIM: 614168
PCK2
phosphoenolpyruvate carboxykinase 2, mitochondrial
Disease-causing germline mutation(s) in
OMIM: 614095

Фенотипы (22)

Очень частый (80–99%)1
HP:0001988Recurrent hypoglycemia
Частый (30–79%)9
HP:0002151Increased circulating lactate concentration
HP:0002173Hypoglycemic seizures
HP:0003128Lactic acidosis
HP:0003217Hyperglutaminemia
HP:0003648Lacticaciduria
HP:0012402Increased urine alpha-ketoglutarate concentration
HP:0031956Elevated circulating aspartate aminotransferase concentration
HP:0031964Elevated circulating alanine aminotransferase concentration
HP:0034648Elevated urine fumaric acid level
Периодический (5–29%)10
HP:0012758Neurodevelopmental delay
HP:0001252Hypotonia
HP:0001254Lethargy
HP:0001325Hypoglycemic coma
HP:0001397Hepatic steatosis
HP:0001410Decreased liver function
HP:0001998Neonatal hypoglycemia
HP:0002013Vomiting
HP:0002329Drowsiness
HP:0006846Acute encephalopathy
Очень редкий (1–4%)2
HP:0000252Microcephaly
HP:0001987Hyperammonemia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы