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Romano-Ward syndrome

ORPHA:101016DiseaseAutosomal dominant, Autosomal recessiveAll ages

Ассоциированные гены (19)

TRDN
triadin
Disease-causing germline mutation(s) in
OMIM: 603283
KCNH2
potassium voltage-gated channel subfamily H member 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 152427
KCNQ1
potassium voltage-gated channel subfamily Q member 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 607542
CAV3
caveolin 3
Disease-causing germline mutation(s) (gain of function) in
OMIM: 601253
ANK2
ankyrin 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 106410
KCNE1
potassium voltage-gated channel subfamily E regulatory subunit 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 176261
KCNE2
potassium voltage-gated channel subfamily E regulatory subunit 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 603796
SCN5A
sodium voltage-gated channel alpha subunit 5
Disease-causing germline mutation(s) (gain of function) in
OMIM: 600163
AKAP9
A-kinase anchoring protein 9
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604001
SCN4B
sodium voltage-gated channel beta subunit 4
Disease-causing germline mutation(s) (gain of function) in
OMIM: 608256
SNTA1
syntrophin alpha 1
Disease-causing germline mutation(s) (gain of function) in
OMIM: 601017
KCNJ5
potassium inwardly rectifying channel subfamily J member 5
Disease-causing germline mutation(s) (loss of function) in
OMIM: 600734
NOS1AP
nitric oxide synthase 1 adaptor protein
Modifying germline mutation in
OMIM: 605551
CALM1
calmodulin 1
Disease-causing germline mutation(s) in
OMIM: 114180
CALM2
calmodulin 2
Disease-causing germline mutation(s) in
OMIM: 114182
SCN10A
sodium voltage-gated channel alpha subunit 10
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604427
TBX5
T-box transcription factor 5
Disease-causing germline mutation(s) (loss of function) in
OMIM: 601620
CACNA1C
calcium voltage-gated channel subunit alpha1 C
Disease-causing germline mutation(s) in
OMIM: 114205
CALM3
calmodulin 3
Disease-causing germline mutation(s) in
OMIM: 114183

Фенотипы (13)

Облигатный (100%)1
HP:0005184Prolonged QTc interval
Частый (30–79%)3
HP:0001279Syncope
HP:0001688Sinus bradycardia
HP:0005135Abnormal T-wave
Периодический (5–29%)6
HP:0001250Seizure
HP:0001645Sudden cardiac death
HP:0001664Torsade de pointes
HP:0004308Ventricular arrhythmia
HP:0012332Abnormal autonomic nervous system physiology
HP:0500018Abnormal cardiac exercise stress test
Очень редкий (1–4%)2
HP:0001197Abnormality of prenatal development or birth
HP:0002900Hypokalemia
Исключён (0%)1
HP:0000365Hearing impairment

Эпидемиология (1)

Point prevalence
1-5 / 10 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы