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Enamel-renal syndrome

ORPHA:1031Malformation syndromeAutosomal recessiveChildhood

Ассоциированные гены (1)

FAM20A
FAM20A golgi associated secretory pathway pseudokinase
Disease-causing germline mutation(s) in
OMIM: 611062

Фенотипы (26)

Очень частый (80–99%)10
HP:0000112Nephropathy
HP:0000121Nephrocalcinosis
HP:0000212Gingival overgrowth
HP:0000682Abnormality of dental enamel
HP:0000684Delayed eruption of teeth
HP:0000705Amelogenesis imperfecta
HP:0006286Yellow-brown discoloration of the teeth
HP:0011073Abnormality of dental color
HP:0031428Increased circulating osteocalcin level
HP:0100530Abnormality of calcium-phosphate metabolism
Частый (30–79%)10
HP:0000083Renal insufficiency
HP:0000169Gingival fibromatosis
HP:0000805Enuresis
HP:0003127Hypocalciuria
HP:0003155Elevated circulating alkaline phosphatase concentration
HP:0003771Pulp calcification
HP:0004727Impaired renal concentrating ability
HP:0011079Impacted tooth
HP:0012365Hypophosphaturia
HP:0012405Hypocitraturia
Периодический (5–29%)5
HP:0000158Macroglossia
HP:0000704Periodontitis
HP:0009102Anterior open-bite malocclusion
HP:0009804Tooth agenesis
HP:0012101Decreased serum creatinine
Очень редкий (1–4%)1
HP:0011069Supernumerary tooth

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы