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Aplasia cutis congenita

ORPHA:1114Malformation syndromeAutosomal dominant, Autosomal recessive, Not applicableAntenatal, Neonatal

Ассоциированные гены (5)

PLEC
plectin
Disease-causing germline mutation(s) in
OMIM: 601282
ITGB4
integrin subunit beta 4
Disease-causing germline mutation(s) in
OMIM: 147557
BMS1
BMS1 ribosome biogenesis factor
Disease-causing germline mutation(s) in
OMIM: 611448
DLL4
delta like canonical Notch ligand 4
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605185
UBA2
ubiquitin like modifier activating enzyme 2
Disease-causing germline mutation(s) in
OMIM: 613295

Фенотипы (13)

Очень частый (80–99%)5
HP:0001057Aplasia cutis congenita
HP:0001362Skull defect
HP:0004471Aplasia cutis congenita over the scalp vertex
HP:0007383Congenital localized absence of skin
HP:0010301Spinal dysraphism
Частый (30–79%)1
HP:0200042Skin ulcer
Периодический (5–29%)7
HP:0001770Toe syndactyly
HP:0003010Prolonged bleeding time
HP:0004348Abnormality of bone mineral density
HP:0006101Finger syndactyly
HP:0010628Facial palsy
HP:0010783Erythema
HP:5200061Tactile hypersensitivity

Эпидемиология (3)

Point prevalence
1-5 / 10 000
Worldwide
Prevalence at birth
1-5 / 10 000
Worldwide
Prevalence at birth
1-9 / 100 000
Denmark

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы