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X-linked progressive cerebellar ataxia

ORPHA:1175DiseaseX-linked recessiveChildhood

Ассоциированные гены (1)

GJB1
gap junction protein beta 1
Disease-causing germline mutation(s) in
OMIM: 304040

Фенотипы (26)

Очень частый (80–99%)1
HP:0002073Progressive cerebellar ataxia
Частый (30–79%)22
HP:0000639Nystagmus
HP:0001152Saccadic smooth pursuit
HP:0001270Motor delay
HP:0001310Dysmetria
HP:0001347Hyperreflexia
HP:0001761Pes cavus
HP:0002070Limb ataxia
HP:0002075Dysdiadochokinesis
HP:0002080Intention tremor
HP:0002312Clumsiness
HP:0002317Unsteady gait
HP:0002359Frequent falls
HP:0002464Spastic dysarthria
HP:0002503Spinocerebellar tract degeneration
HP:0002650Scoliosis
HP:0003445EMG: neuropathic changes
HP:0003447Axonal loss
HP:0006855Cerebellar vermis atrophy
HP:0007141Sensorimotor neuropathy
HP:0007240Progressive gait ataxia
HP:0008944Distal lower limb amyotrophy
HP:0200101Decreased/absent ankle reflexes
Периодический (5–29%)3
HP:0002395Lower limb hyperreflexia
HP:0003487Babinski sign
HP:0009027Foot dorsiflexor weakness

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы