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Branchio-oculo-facial syndrome

ORPHA:1297Malformation syndromeAutosomal dominantAntenatal, Neonatal

Ассоциированные гены (1)

TFAP2A
transcription factor AP-2 alpha
Disease-causing germline mutation(s) in
OMIM: 107580

Фенотипы (37)

Очень частый (80–99%)11
HP:0000358Posteriorly rotated ears
HP:0000232Everted lower lip vermilion
HP:0000377Abnormal pinna morphology
HP:0000405Conductive hearing impairment
HP:0000589Coloboma
HP:0000987Atypical scarring of skin
HP:0001028Hemangioma
HP:0002002Deep philtrum
HP:0004464Postauricular pit
HP:0004467Preauricular pit
HP:0008606Supraauricular pit
Частый (30–79%)16
HP:0000218High palate
HP:0000268Dolichocephaly
HP:0000431Wide nasal bridge
HP:0000455Broad nasal tip
HP:0000579Nasolacrimal duct obstruction
HP:0000582Upslanted palpebral fissure
HP:0000612Iris coloboma
HP:0000691Microdontia
HP:0001511Intrauterine growth retardation
HP:0001611Hypernasal speech
HP:0002167Abnormality of speech or vocalization
HP:0002216Premature graying of hair
HP:0004322Short stature
HP:0009804Tooth agenesis
HP:0100335Non-midline cleft of the upper lip
HP:0100798Fingernail dysplasia
Периодический (5–29%)10
HP:0000003Multicystic kidney dysplasia
HP:0000104Renal agenesis
HP:0000126Hydronephrosis
HP:0000202Orofacial cleft
HP:0000482Microcornea
HP:0000486Strabismus
HP:0000508Ptosis
HP:0000518Cataract
HP:0001177Preaxial hand polydactyly
HP:0100268Upper lip pit

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы