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Leukoencephalopathy with brain stem and spinal cord involvement-high lactate syndrome

ORPHA:137898DiseaseAutosomal recessiveAdolescent, Adult, Antenatal, Childhood, Infancy, Neonatal

Ассоциированные гены (1)

DARS2
aspartyl-tRNA synthetase 2, mitochondrial
Disease-causing germline mutation(s) in
OMIM: 610956

Фенотипы (50)

Очень частый (80–99%)1
HP:0011397Abnormality of the dorsal column of the spinal cord
Частый (30–79%)15
HP:0003487Babinski sign
HP:0001260Dysarthria
HP:0001288Gait disturbance
HP:0001317Abnormal cerebellum morphology
HP:0001337Tremor
HP:0002073Progressive cerebellar ataxia
HP:0002167Abnormality of speech or vocalization
HP:0002191Progressive spasticity
HP:0002312Clumsiness
HP:0002317Unsteady gait
HP:0002460Distal muscle weakness
HP:0002493Upper motor neuron dysfunction
HP:0002497Spastic ataxia
HP:0002505Loss of ambulation
HP:0006978Dysmyelinating leukodystrophy
Периодический (5–29%)13
HP:0001265Hyporeflexia
HP:0001268Mental deterioration
HP:0001270Motor delay
HP:0001315Reduced tendon reflexes
HP:0001328Specific learning disability
HP:0002151Increased circulating lactate concentration
HP:0002166Impaired vibration sensation in the lower limbs
HP:0002490Increased CSF lactate
HP:0003477Peripheral axonal neuropathy
HP:0006858Impaired distal proprioception
HP:0007010Poor fine motor coordination
HP:0008969Leg muscle stiffness
HP:0010794Impaired visuospatial constructive cognition
Очень редкий (1–4%)21
HP:0000365Hearing impairment
HP:0000508Ptosis
HP:0000514Slow saccadic eye movements
HP:0000639Nystagmus
HP:0000648Optic atrophy
HP:0000651Diplopia
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001252Hypotonia
HP:0001271Polyneuropathy
HP:0001272Cerebellar atrophy
HP:0001276Hypertonia
HP:0001344Absent speech
HP:0001350Slurred speech
HP:0001371Flexion contracture
HP:0002059Cerebral atrophy
HP:0002078Truncal ataxia
HP:0002079Hypoplasia of the corpus callosum
HP:0005340Spastic/hyperactive bladder
HP:0007668Impaired pursuit initiation and maintenance
HP:0009055Generalized limb muscle atrophy

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы