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Knobloch syndrome

ORPHA:1571Malformation syndromeAutosomal recessiveAntenatal, Infancy, Neonatal

Ассоциированные гены (2)

PAK2
p21 (RAC1) activated kinase 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605022
COL18A1
collagen type XVIII alpha 1 chain
Disease-causing germline mutation(s) in
OMIM: 120328

Фенотипы (26)

Очень частый (80–99%)5
HP:0000541Retinal detachment
HP:0000545Myopia
HP:0000608Macular degeneration
HP:0001362Skull defect
HP:0002085Occipital encephalocele
Частый (30–79%)6
HP:0000238Hydrocephalus
HP:0000529Progressive visual loss
HP:0000572Visual loss
HP:0000639Nystagmus
HP:0004327Abnormal vitreous humor morphology
HP:0007773Vitreoretinopathy
Периодический (5–29%)15
HP:0001382Joint hypermobility
HP:0000076Vesicoureteral reflux
HP:0000286Epicanthus
HP:0000486Strabismus
HP:0000518Cataract
HP:0001083Ectopia lentis
HP:0001250Seizure
HP:0001595Abnormality of the hair
HP:0001643Patent ductus arteriosus
HP:0001651Dextrocardia
HP:0002021Pyloric stenosis
HP:0005280Depressed nasal bridge
HP:0011800Midface retrusion
HP:0030037Bifid ureter
HP:0100764Lymphangioma

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы