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Wolcott-Rallison syndrome

ORPHA:1667DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

EIF2AK3
eukaryotic translation initiation factor 2 alpha kinase 3
Disease-causing germline mutation(s) in
OMIM: 604032

Фенотипы (40)

Очень частый (80–99%)5
HP:0000857Neonatal insulin-dependent diabetes mellitus
HP:0001392Abnormality of the liver
HP:0001510Growth delay
HP:0002652Skeletal dysplasia
HP:0004322Short stature
Частый (30–79%)7
HP:0001875Decreased total neutrophil count
HP:0002654Multiple epiphyseal dysplasia
HP:0002910Elevated circulating hepatic transaminase concentration
HP:0003073Hypoalbuminemia
HP:0004325Decreased body weight
HP:0006554Acute hepatic failure
HP:0100255Metaphyseal dysplasia
Периодический (5–29%)23
HP:0000083Renal insufficiency
HP:0000252Microcephaly
HP:0000486Strabismus
HP:0000821Hypothyroidism
HP:0000952Jaundice
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001263Global developmental delay
HP:0001324Muscle weakness
HP:0001738Exocrine pancreatic insufficiency
HP:0001891Iron deficiency anemia
HP:0001944Dehydration
HP:0001945Fever
HP:0001987Hyperammonemia
HP:0001993Ketoacidosis
HP:0002240Hepatomegaly
HP:0002719Recurrent infections
HP:0002904Hyperbilirubinemia
HP:0011787Central hypothyroidism
HP:0012622Chronic kidney disease
HP:0100827Lymphocytosis
HP:0410263Brain imaging abnormality
HP:0001288Gait disturbance
Очень редкий (1–4%)5
HP:0001541Ascites
HP:0001631Atrial septal defect
HP:0001719Double outlet right ventricle
HP:0002480Hepatic encephalopathy
HP:0002902Hyponatremia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы