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Cushing syndrome due to bilateral macronodular adrenocortical disease

ORPHA:189427DiseaseAutosomal dominant, Not applicableAll ages

Ассоциированные гены (3)

KDM1A
lysine demethylase 1A
Modifying germline mutation in
OMIM: 609132
GNAS
GNAS complex locus
Disease-causing somatic mutation(s) in
OMIM: 139320
ARMC5
armadillo repeat containing 5
Disease-causing germline mutation(s) in
OMIM: 615549

Фенотипы (39)

Облигатный (100%)1
HP:0008231Macronodular adrenal hyperplasia
Очень частый (80–99%)2
HP:0002920Decreased circulating ACTH level
HP:0500011Moon facies
Частый (30–79%)21
HP:0000712Emotional lability
HP:0000716Depression
HP:0000787Nephrolithiasis
HP:0000822Hypertension
HP:0000858Irregular menstruation
HP:0000939Osteoporosis
HP:0000978Bruising susceptibility
HP:0001007Hirsutism
HP:0001050Plethora
HP:0001065Striae distensae
HP:0001952Glucose intolerance
HP:0003077Hyperlipidemia
HP:0003118Increased circulating cortisol level
HP:0003466Paradoxical increased cortisol secretion on dexamethasone suppression test
HP:0003701Proximal muscle weakness
HP:0007126Proximal amyotrophy
HP:0012030Increased urinary cortisol level
HP:0012743Abdominal obesity
HP:0025383Dorsocervical fat pad
HP:0031077Abnormal response to corticotropin releasing hormone stimulation test
HP:0031845Abnormal libido
Периодический (5–29%)8
HP:0000725Psychotic episodes
HP:0001061Acne
HP:0001397Hepatic steatosis
HP:0001596Alopecia
HP:0002354Memory impairment
HP:0002659Increased susceptibility to fractures
HP:0004324Increased body weight
HP:0100754Mania
Очень редкий (1–4%)7
HP:0000859Hyperaldosteronism
HP:0002858Meningioma
HP:0002893Pituitary adenoma
HP:0005584Renal cell carcinoma
HP:0008200Primary hyperparathyroidism
HP:0100543Cognitive impairment
HP:0100634Neuroendocrine neoplasm

Эпидемиология (1)

Point prevalence
<1 / 1 000 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы