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Bilateral striopallidodentate calcinosis

ORPHA:1980DiseaseAutosomal dominant, Autosomal recessive, Not applicableAdult

Ассоциированные гены (8)

NAA60
N-alpha-acetyltransferase 60, NatF catalytic subunit
Disease-causing germline mutation(s) (loss of function) in
OMIM: 614246
CMPK2
cytidine/uridine monophosphate kinase 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 611787
JAM2
junctional adhesion molecule 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 606870
MYORG
myogenesis regulating glycosidase
Disease-causing germline mutation(s) in
OMIM: 618255
PDGFRB
platelet derived growth factor receptor beta
Disease-causing germline mutation(s) in
OMIM: 173410
PDGFB
platelet derived growth factor subunit B
Disease-causing germline mutation(s) (loss of function) in
OMIM: 190040
SLC20A2
solute carrier family 20 member 2
Disease-causing germline mutation(s) in
OMIM: 158378
XPR1
xenotropic and polytropic retrovirus receptor 1
Disease-causing germline mutation(s) in
OMIM: 605237

Фенотипы (33)

Частый (30–79%)15
HP:0000298Mask-like facies
HP:0000709Psychosis
HP:0000726Dementia
HP:0000739Anxiety
HP:0000751Personality changes
HP:0001250Seizure
HP:0001266Choreoathetosis
HP:0001337Tremor
HP:0002063Rigidity
HP:0002067Bradykinesia
HP:0002135Basal ganglia calcification
HP:0002315Headache
HP:0002321Vertigo
HP:0002344Progressive neurologic deterioration
HP:0007146Bilateral basal ganglia lesions
Периодический (5–29%)16
HP:0000012Urinary urgency
HP:0000802Impotence
HP:0000822Hypertension
HP:0001332Dystonia
HP:0001350Slurred speech
HP:0002015Dysphagia
HP:0002312Clumsiness
HP:0002317Unsteady gait
HP:0002354Memory impairment
HP:0003388Easy fatigability
HP:0100660Dyskinesia
HP:0003394Muscle spasm
HP:0004305Involuntary movements
HP:0007256Abnormal pyramidal sign
HP:0007352Cerebellar calcifications
HP:0031987Diminished ability to concentrate
Исключён (0%)2
HP:0011450Unusual CNS infection
HP:0032180Abnormal circulating metabolite concentration

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы