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Gamma-aminobutyric acid transaminase deficiency

ORPHA:2066DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

ABAT
4-aminobutyrate aminotransferase
Disease-causing germline mutation(s) in
OMIM: 137150

Фенотипы (22)

Облигатный (100%)1
HP:0200134Epileptic encephalopathy
Очень частый (80–99%)7
HP:0001252Hypotonia
HP:0002353EEG abnormality
HP:0007266Cerebral dysmyelination
HP:0011344Severe global developmental delay
HP:0032531Elevated CSF gamma-aminobutyric acid concentration
HP:0410053Elevated circulating gamma-aminobutyric acid concentration
HP:0500253Increased level of gamma-aminobutyric acid in urine
Частый (30–79%)11
HP:0000098Tall stature
HP:0000845Elevated circulating growth hormone concentration
HP:0001250Seizure
HP:0001266Choreoathetosis
HP:0001347Hyperreflexia
HP:0001508Failure to thrive
HP:0002059Cerebral atrophy
HP:0007272Progressive psychomotor deterioration
HP:0008872Feeding difficulties in infancy
HP:0025430High-pitched cry
HP:0100786Hypersomnia
Периодический (5–29%)3
HP:0001254Lethargy
HP:0001272Cerebellar atrophy
HP:0001273Abnormal corpus callosum morphology

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы