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Familial cerebral cavernous malformation

ORPHA:221061Malformation syndromeAutosomal dominantAll ages

Ассоциированные гены (4)

CCM2
CCM2 scaffold protein
Disease-causing germline mutation(s) (loss of function) in
OMIM: 607929
KRIT1
KRIT1 ankyrin repeat containing
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604214
PDCD10
programmed cell death 10
Disease-causing germline mutation(s) in
OMIM: 609118
PIK3CA
phosphatidylinositol-4,5-bisphosphate 3-kinase catalytic subunit alpha
Disease-causing somatic mutation(s) in
OMIM: 171834

Фенотипы (25)

Облигатный (100%)1
HP:0033522Cerebral cavernous malformation
Очень частый (80–99%)3
HP:0001250Seizure
HP:0001342Cerebral hemorrhage
HP:0002315Headache
Частый (30–79%)10
HP:0001028Hemangioma
HP:0001048Cavernous hemangioma
HP:0001324Muscle weakness
HP:0002516Increased intracranial pressure
HP:0002650Scoliosis
HP:0003401Paresthesia
HP:0012748Focal T2 hyperintense brainstem lesion
HP:0012749Focal T2 hypointense brainstem lesion
HP:0030430Neuroma
HP:0033748Hypoesthesia
Периодический (5–29%)7
HP:0100561Spinal cord lesion
HP:0002572Episodic vomiting
HP:0007872Choroidal hemangioma
HP:0011276Vascular skin abnormality
HP:0011513Retinal cavernous angioma
HP:0012721Venous malformation
HP:0100543Cognitive impairment
Очень редкий (1–4%)4
HP:0002858Meningioma
HP:0009588Vestibular schwannoma
HP:0009592Astrocytoma
HP:0010512Adrenal calcification

Эпидемиология (1)

Point prevalence
1-5 / 10 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы