← Назад

Familial infantile bilateral striatal necrosis

ORPHA:225154DiseaseAutosomal dominant, Autosomal recessive, Mitochondrial inheritanceInfancy, Neonatal

Ассоциированные гены (4)

NUP54
nucleoporin 54
Disease-causing germline mutation(s) in
OMIM: 607607
ADAR
adenosine deaminase RNA specific
Disease-causing germline mutation(s) (loss of function) in
OMIM: 146920
MT-ATP6
mitochondrially encoded ATP synthase membrane subunit 6
Disease-causing germline mutation(s) in
OMIM: 516060
NUP62
nucleoporin 62
Disease-causing germline mutation(s) in
OMIM: 605815

Фенотипы (36)

Частый (30–79%)23
HP:0002273Tetraparesis
HP:0002376Developmental regression
HP:0003487Babinski sign
HP:0006999Basal ganglia gliosis
HP:0007374Atrophy/Degeneration involving the caudate nucleus
HP:0007811Horizontal pendular nystagmus
HP:0008947Floppy infant
HP:0012758Neurodevelopmental delay
HP:0000648Optic atrophy
HP:0000750Delayed speech and language development
HP:0001251Ataxia
HP:0001256Intellectual disability, mild
HP:0001257Spasticity
HP:0001260Dysarthria
HP:0001266Choreoathetosis
HP:0001285Spastic tetraparesis
HP:0001288Gait disturbance
HP:0001332Dystonia
HP:0001347Hyperreflexia
HP:0001508Failure to thrive
HP:0002015Dysphagia
HP:0002066Gait ataxia
HP:0002167Abnormality of speech or vocalization
Периодический (5–29%)13
HP:0001276Hypertonia
HP:0001336Myoclonus
HP:0002020Gastroesophageal reflux
HP:0002063Rigidity
HP:0002359Frequent falls
HP:0002396Cogwheel rigidity
HP:0002446Astrocytosis
HP:0002505Loss of ambulation
HP:0003484Upper limb muscle weakness
HP:0006799Basal ganglia cysts
HP:0007340Lower limb muscle weakness
HP:0007688Undetectable light- and dark-adapted electroretinogram
HP:0012697Small basal ganglia

Эпидемиология (1)

Point prevalence
<1 / 1 000 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы