← Назад

Hypothyroidism due to deficient transcription factors involved in pituitary development or function

ORPHA:226307DiseaseAutosomal dominant, Autosomal recessiveInfancy

Ассоциированные гены (5)

POU1F1
POU class 1 homeobox 1
Disease-causing germline mutation(s) in
OMIM: 173110
PROP1
PROP paired-like homeobox 1
Disease-causing germline mutation(s) in
OMIM: 601538
HESX1
HESX homeobox 1
Disease-causing germline mutation(s) in
OMIM: 601802
LHX3
LIM homeobox 3
Disease-causing germline mutation(s) in
OMIM: 600577
LHX4
LIM homeobox 4
Disease-causing germline mutation(s) in
OMIM: 602146

Фенотипы (51)

Очень частый (80–99%)3
HP:0008245Pituitary hypothyroidism
HP:0031098Decreased thyroid-stimulating hormone level
HP:0031219Reduced radioactive iodine uptake
Частый (30–79%)23
HP:0000158Macroglossia
HP:0000270Delayed cranial suture closure
HP:0000282Facial edema
HP:0000871Panhypopituitarism
HP:0001254Lethargy
HP:0001265Hyporeflexia
HP:0001510Growth delay
HP:0001537Umbilical hernia
HP:0001662Bradycardia
HP:0002019Constipation
HP:0002045Hypothermia
HP:0004491Large posterior fontanelle
HP:0005930Abnormality of epiphysis morphology
HP:0005990Thyroid hypoplasia
HP:0006579Prolonged neonatal jaundice
HP:0008202Reduced circulating prolactin concentration
HP:0008828Delayed proximal femoral epiphyseal ossification
HP:0008872Feeding difficulties in infancy
HP:0010627Anterior pituitary hypoplasia
HP:0012378Fatigue
HP:0012758Neurodevelopmental delay
HP:0031507Decreased circulating thyroxine level
HP:0040075Hypopituitarism
Периодический (5–29%)23
HP:0000044Hypogonadotropic hypogonadism
HP:0000407Sensorineural hearing impairment
HP:0000470Short neck
HP:0000609Optic nerve hypoplasia
HP:0000824Decreased response to growth hormone stimulation test
HP:0000839Pituitary dwarfism
HP:0001161Hand polydactyly
HP:0001252Hypotonia
HP:0001274Agenesis of corpus callosum
HP:0001317Abnormal cerebellum morphology
HP:0001943Hypoglycemia
HP:0001999Abnormal facial shape
HP:0002920Decreased circulating ACTH level
HP:0004637Decreased cervical spine mobility
HP:0005280Depressed nasal bridge
HP:0009381Short finger
HP:0011220Prominent forehead
HP:0011755Ectopic posterior pituitary
HP:0011800Midface retrusion
HP:0025502Overweight
HP:0030341Decreased circulating follicle stimulating hormone concentration
HP:0030344Decreased circulating luteinizing hormone level
HP:0031218Inappropriate antidiuretic hormone secretion
Исключён (0%)2
HP:0011437Maternal autoimmune disease
HP:0025483Abnormal circulating thyroglobulin concentration

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы