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Johanson-Blizzard syndrome

ORPHA:2315Malformation syndromeAutosomal recessiveAntenatal, Infancy, Neonatal

Ассоциированные гены (1)

UBR1
ubiquitin protein ligase E3 component n-recognin 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605981

Фенотипы (37)

Очень частый (80–99%)11
HP:0000164Abnormality of the dentition
HP:0000430Underdeveloped nasal alae
HP:0001508Failure to thrive
HP:0001511Intrauterine growth retardation
HP:0001596Alopecia
HP:0001732Abnormality of the pancreas
HP:0001738Exocrine pancreatic insufficiency
HP:0002024Malabsorption
HP:0003196Short nose
HP:0004322Short stature
HP:0010720Abnormal hair pattern
Частый (30–79%)14
HP:0000142Abnormality of the vagina
HP:0000407Sensorineural hearing impairment
HP:0000632Lacrimation abnormality
HP:0000677Oligodontia
HP:0000684Delayed eruption of teeth
HP:0000691Microdontia
HP:0001092Absent lacrimal punctum
HP:0001249Intellectual disability
HP:0001545Anteriorly placed anus
HP:0001903Anemia
HP:0002023Anal atresia
HP:0002750Delayed skeletal maturation
HP:0003075Hypoproteinemia
HP:0010460Abnormality of the female genitalia
Периодический (5–29%)12
HP:0000047Hypospadias
HP:0000126Hydronephrosis
HP:0000252Microcephaly
HP:0000819Diabetes mellitus
HP:0000969Edema
HP:0001252Hypotonia
HP:0001522Death in infancy
HP:0001651Dextrocardia
HP:0001671Abnormal cardiac septum morphology
HP:0005288Abnormality of the nares
HP:0008736Hypoplasia of penis
HP:0030680Abnormal cardiovascular system morphology

Эпидемиология (2)

Prevalence at birth
1-9 / 1 000 000
Europe
Point prevalence
Unknown
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы