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Combined oxidative phosphorylation defect type 7

ORPHA:254930DiseaseAutosomal recessiveChildhood, Infancy

Ассоциированные гены (1)

MTRFR
mitochondrial translation release factor in rescue
Disease-causing germline mutation(s) in
OMIM: 613541

Фенотипы (42)

Очень частый (80–99%)3
HP:0000505Visual impairment
HP:0000648Optic atrophy
HP:0003202Skeletal muscle atrophy
Частый (30–79%)15
HP:0000602Ophthalmoplegia
HP:0001123Visual field defect
HP:0001263Global developmental delay
HP:0001288Gait disturbance
HP:0001508Failure to thrive
HP:0001761Pes cavus
HP:0002313Spastic paraparesis
HP:0002395Lower limb hyperreflexia
HP:0002936Distal sensory impairment
HP:0003477Peripheral axonal neuropathy
HP:0003693Distal amyotrophy
HP:0007256Abnormal pyramidal sign
HP:0007340Lower limb muscle weakness
HP:0031629Impaired tandem gait
HP:0100543Cognitive impairment
Периодический (5–29%)24
HP:0000508Ptosis
HP:0000639Nystagmus
HP:0001251Ataxia
HP:0001260Dysarthria
HP:0001283Bulbar palsy
HP:0001284Areflexia
HP:0001349Facial diplegia
HP:0002079Hypoplasia of the corpus callosum
HP:0002376Developmental regression
HP:0002500Abnormal cerebral white matter morphology
HP:0002540Inability to walk
HP:0002590Paralytic ileus
HP:0002943Thoracic scoliosis
HP:0003380Decreased number of peripheral myelinated nerve fibers
HP:0003484Upper limb muscle weakness
HP:0005216Impaired mastication
HP:0007641Dyschromatopsia
HP:0008947Floppy infant
HP:0011471Gastrostomy tube feeding in infancy
HP:0012696Abnormal thalamic MRI signal intensity
HP:0012707Elevated brain lactate level by MRS
HP:0012747Abnormal brainstem MRI signal intensity
HP:0020049Exodeviation
HP:0200136Oral-pharyngeal dysphagia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы