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Ataxia-pancytopenia syndrome

ORPHA:2585Malformation syndromeAutosomal dominantAdolescent, Adult, Childhood

Ассоциированные гены (1)

SAMD9L
sterile alpha motif domain containing 9 like
Disease-causing germline mutation(s) in
OMIM: 611170

Фенотипы (18)

Очень частый (80–99%)5
HP:0001251Ataxia
HP:0001272Cerebellar atrophy
HP:0001288Gait disturbance
HP:0002317Unsteady gait
HP:0007360Aplasia/Hypoplasia of the cerebellum
Частый (30–79%)9
HP:0000639Nystagmus
HP:0001347Hyperreflexia
HP:0001744Splenomegaly
HP:0001874Abnormality of neutrophils
HP:0001908Hypoplastic anemia
HP:0002167Abnormality of speech or vocalization
HP:0002205Recurrent respiratory infections
HP:0004311Abnormal macrophage morphology
HP:0004820Acute myelomonocytic leukemia
Периодический (5–29%)4
HP:0000252Microcephaly
HP:0001876Pancytopenia
HP:0004313Decreased circulating antibody level
HP:0011869Abnormal platelet function

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы