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Short chain acyl-CoA dehydrogenase deficiency

ORPHA:26792DiseaseAutosomal recessiveChildhood, Infancy, Neonatal

Ассоциированные гены (1)

ACADS
acyl-CoA dehydrogenase short chain
Disease-causing germline mutation(s) in
OMIM: 606885

Фенотипы (24)

Частый (30–79%)8
HP:0001508Failure to thrive
HP:0001942Metabolic acidosis
HP:0003219Ethylmalonic aciduria
HP:0008947Floppy infant
HP:0011968Feeding difficulties
HP:0012758Neurodevelopmental delay
HP:0045045Elevated plasma acylcarnitine levels
HP:0410153Increased level of methylsuccinic acid in urine
Периодический (5–29%)12
HP:0000708Atypical behavior
HP:0000750Delayed speech and language development
HP:0001250Seizure
HP:0001254Lethargy
HP:0001332Dystonia
HP:0001397Hepatic steatosis
HP:0001638Cardiomyopathy
HP:0001999Abnormal facial shape
HP:0002098Respiratory distress
HP:0003198Myopathy
HP:0006929Hypoglycemic encephalopathy
HP:0012734Ketotic hypoglycemia
Очень редкий (1–4%)4
HP:0000252Microcephaly
HP:0000648Optic atrophy
HP:0001276Hypertonia
HP:0001511Intrauterine growth retardation

Эпидемиология (2)

Point prevalence
Unknown
Worldwide
Prevalence at birth
1-9 / 100 000
Netherlands

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы