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Oculopharyngeal muscular dystrophy

ORPHA:270DiseaseAutosomal dominant, Autosomal recessiveAdult, Elderly

Ассоциированные гены (1)

PABPN1
poly(A) binding protein nuclear 1
Disease-causing germline mutation(s) in
OMIM: 602279

Фенотипы (26)

Очень частый (80–99%)9
HP:0000508Ptosis
HP:0000602Ophthalmoplegia
HP:0002015Dysphagia
HP:0003198Myopathy
HP:0003200Ragged-red muscle fibers
HP:0003302Spondylolisthesis
HP:0003805Rimmed vacuoles
HP:0004303Abnormal muscle fiber morphology
HP:0012378Fatigue
Частый (30–79%)13
HP:0000183Tongue muscle weakness
HP:0001618Dysphonia
HP:0003325Limb-girdle muscle weakness
HP:0003327Axial muscle weakness
HP:0011968Feeding difficulties
HP:0012473Tongue atrophy
HP:0012531Pain
HP:0012548Fatty replacement of skeletal muscle
HP:0030319Weakness of facial musculature
HP:0032342Reduced forced expiratory volume in one second
HP:0034045Angulated muscle fibers
HP:0100304Muscle fiber intranuclear inclusion bodies
HP:6001011Wet voice
Периодический (5–29%)2
HP:0000298Mask-like facies
HP:0003236Elevated circulating creatine kinase concentration
Очень редкий (1–4%)2
HP:0010535Sleep apnea
HP:0100543Cognitive impairment

Эпидемиология (4)

Point prevalence
>1 / 1000
Specific population
Point prevalence
1-9 / 100 000
France
Point prevalence
1-9 / 100 000
Europe
Point prevalence
>1 / 1000
Specific population

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы