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Autosomal dominant hyperinsulinism due to Kir6.2 deficiency

ORPHA:276580DiseaseAutosomal dominantInfancy, Neonatal

Ассоциированные гены (1)

KCNJ11
potassium inwardly rectifying channel subfamily J member 11
Disease-causing germline mutation(s) in
OMIM: 600937

Фенотипы (29)

Очень частый (80–99%)6
HP:0000825Hyperinsulinemic hypoglycemia
HP:0000842Hyperinsulinemia
HP:0001985Hypoketotic hypoglycemia
HP:0003162Fasting hypoglycemia
HP:0030796Increased C-peptide level
HP:0031084Excessive insulin response to glucagon test
Частый (30–79%)11
HP:0000713Agitation
HP:0000980Pallor
HP:0001069Episodic hyperhidrosis
HP:0001520Large for gestational age
HP:0001649Tachycardia
HP:0001962Palpitations
HP:0002173Hypoglycemic seizures
HP:0002329Drowsiness
HP:0004924Abnormal oral glucose tolerance
HP:0012759Neurodevelopmental abnormality
HP:0031224Diffuse pancreatic islet hyperplasia
Периодический (5–29%)11
HP:0001254Lethargy
HP:0001279Syncope
HP:0001324Muscle weakness
HP:0001325Hypoglycemic coma
HP:0001639Hypertrophic cardiomyopathy
HP:0002133Status epilepticus
HP:0002240Hepatomegaly
HP:0002591Polyphagia
HP:0007185Loss of consciousness
HP:0009800Maternal diabetes
HP:0011968Feeding difficulties
Очень редкий (1–4%)1
HP:0100651Type I diabetes mellitus

Эпидемиология (1)

Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы