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X-linked sideroblastic anemia and spinocerebellar ataxia

ORPHA:2802DiseaseX-linked recessiveChildhood, Infancy

Ассоциированные гены (1)

ABCB7
ATP binding cassette subfamily B member 7
Disease-causing germline mutation(s) (loss of function) in
OMIM: 300135

Фенотипы (32)

Очень частый (80–99%)6
HP:0001251Ataxia
HP:0001903Anemia
HP:0002066Gait ataxia
HP:0002167Abnormality of speech or vocalization
HP:0012187Increased erythrocyte protoporphyrin concentration
HP:0031936Delayed ability to walk
Частый (30–79%)11
HP:0000486Strabismus
HP:0000639Nystagmus
HP:0000750Delayed speech and language development
HP:0001260Dysarthria
HP:0001347Hyperreflexia
HP:0001348Brisk reflexes
HP:0001924Sideroblastic anemia
HP:0002172Postural instability
HP:0002194Delayed gross motor development
HP:0004840Hypochromic microcytic anemia
HP:0011273Anisocytosis
Периодический (5–29%)9
HP:0000717Autism
HP:0001252Hypotonia
HP:0001272Cerebellar atrophy
HP:0001310Dysmetria
HP:0001510Growth delay
HP:0002075Dysdiadochokinesis
HP:0004447Poikilocytosis
HP:0020081Pappenheimer bodies
HP:0034499Increased bone marrow iron
Очень редкий (1–4%)6
HP:0000028Cryptorchidism
HP:0000716Depression
HP:0001250Seizure
HP:0001992Organic aciduria
HP:0100543Cognitive impairment
HP:0100753Schizophrenia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы