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Alpha-dystroglycan-related limb-girdle muscular dystrophy R16

ORPHA:280333DiseaseAutosomal recessiveChildhood

Ассоциированные гены (1)

DAG1
dystroglycan 1
Disease-causing germline mutation(s) in
OMIM: 128239

Фенотипы (15)

Очень частый (80–99%)3
HP:0003236Elevated circulating creatine kinase concentration
HP:0006785Limb-girdle muscular dystrophy
HP:0030099Reduced muscle fiber alpha dystroglycan
Частый (30–79%)6
HP:0001270Motor delay
HP:0002317Unsteady gait
HP:0002515Waddling gait
HP:0003551Difficulty climbing stairs
HP:0008981Calf muscle hypertrophy
HP:0010864Intellectual disability, severe
Периодический (5–29%)6
HP:0001256Intellectual disability, mild
HP:0002465Poor speech
HP:0002938Lumbar hyperlordosis
HP:0003391Gowers sign
HP:0003707Calf muscle pseudohypertrophy
HP:0006466Ankle flexion contracture

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы