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Recessive intellectual disability-motor dysfunction-multiple joint contractures syndrome

ORPHA:280384DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

ERLIN2
ER lipid raft associated 2
Disease-causing germline mutation(s) in
OMIM: 611605

Фенотипы (20)

Очень частый (80–99%)4
HP:0001344Absent speech
HP:0002376Developmental regression
HP:0003121Limb joint contracture
HP:0010864Intellectual disability, severe
Частый (30–79%)6
HP:0000154Wide mouth
HP:0000158Macroglossia
HP:0002373Febrile seizure (within the age range of 3 months to 6 years)
HP:0002987Elbow flexion contracture
HP:0006380Knee flexion contracture
HP:0006466Ankle flexion contracture
Периодический (5–29%)10
HP:0000218High palate
HP:0000322Short philtrum
HP:0000377Abnormal pinna morphology
HP:0000574Thick eyebrow
HP:0000664Synophrys
HP:0002015Dysphagia
HP:0002378Hand tremor
HP:0007350Hyperreflexia in upper limbs
HP:0011448Ankle clonus
HP:0100712Abnormal lumbar spine morphology

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы