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Early-onset spastic ataxia-myoclonic epilepsy-neuropathy syndrome

ORPHA:313772DiseaseAutosomal recessiveChildhood

Ассоциированные гены (1)

AFG3L2
AFG3 like matrix AAA peptidase subunit 2
Disease-causing germline mutation(s) in
OMIM: 604581

Фенотипы (24)

Частый (30–79%)24
HP:0000508Ptosis
HP:0000657Oculomotor apraxia
HP:0001251Ataxia
HP:0001256Intellectual disability, mild
HP:0001257Spasticity
HP:0001272Cerebellar atrophy
HP:0001310Dysmetria
HP:0001321Cerebellar hypoplasia
HP:0001332Dystonia
HP:0001336Myoclonus
HP:0002015Dysphagia
HP:0002069Bilateral tonic-clonic seizure
HP:0002075Dysdiadochokinesis
HP:0002123Generalized myoclonic seizure
HP:0002313Spastic paraparesis
HP:0002353EEG abnormality
HP:0002460Distal muscle weakness
HP:0002464Spastic dysarthria
HP:0003477Peripheral axonal neuropathy
HP:0003693Distal amyotrophy
HP:0007108Demyelinating peripheral neuropathy
HP:0007141Sensorimotor neuropathy
HP:0007340Lower limb muscle weakness
HP:0008316Abnormal mitochondria in muscle tissue

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы