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Autosomal recessive myogenic arthrogryposis multiplex congenita

ORPHA:319332DiseaseAutosomal recessiveNeonatal

Ассоциированные гены (1)

SYNE1
spectrin repeat containing nuclear envelope protein 1
Disease-causing germline mutation(s) in
OMIM: 608441

Фенотипы (30)

Очень частый (80–99%)9
HP:0001265Hyporeflexia
HP:0001270Motor delay
HP:0001558Decreased fetal movement
HP:0001776Bilateral talipes equinovarus
HP:0002540Inability to walk
HP:0002804Arthrogryposis multiplex congenita
HP:0008935Generalized neonatal hypotonia
HP:0030200Fatiguable weakness of proximal limb muscles
HP:0430025Bilateral facial palsy
Частый (30–79%)2
HP:0000028Cryptorchidism
HP:0002650Scoliosis
Периодический (5–29%)16
HP:0000276Long face
HP:0000343Long philtrum
HP:0000400Macrotia
HP:0000486Strabismus
HP:0001181Adducted thumb
HP:0001188Hand clenching
HP:0001249Intellectual disability
HP:0001518Small for gestational age
HP:0003391Gowers sign
HP:0005191Congenital knee dislocation
HP:0005280Depressed nasal bridge
HP:0005469Flat occiput
HP:0008897Postnatal growth retardation
HP:0011471Gastrostomy tube feeding in infancy
HP:0012785Flexion contracture of finger
HP:0031729Moderate hypermetropia
Исключён (0%)3
HP:0000252Microcephaly
HP:0001561Polyhydramnios
HP:0040081Abnormal circulating creatine kinase concentration

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы