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Autosomal recessive spastic paraplegia type 55

ORPHA:320375DiseaseAutosomal recessiveChildhood

Ассоциированные гены (1)

MTRFR
mitochondrial translation release factor in rescue
Disease-causing germline mutation(s) in
OMIM: 613541

Фенотипы (27)

Частый (30–79%)22
HP:0000648Optic atrophy
HP:0001138Optic neuropathy
HP:0001256Intellectual disability, mild
HP:0001257Spasticity
HP:0001347Hyperreflexia
HP:0001762Talipes equinovarus
HP:0002061Lower limb spasticity
HP:0002079Hypoplasia of the corpus callosum
HP:0002313Spastic paraparesis
HP:0002936Distal sensory impairment
HP:0003202Skeletal muscle atrophy
HP:0003383Onion bulb formation
HP:0003448Decreased sensory nerve conduction velocity
HP:0003484Upper limb muscle weakness
HP:0003487Babinski sign
HP:0007010Poor fine motor coordination
HP:0007042Focal white matter lesions
HP:0007340Lower limb muscle weakness
HP:0007663Reduced visual acuity
HP:0008963Tibialis muscle weakness
HP:0009027Foot dorsiflexor weakness
HP:0009830Peripheral neuropathy
Периодический (5–29%)5
HP:0000486Strabismus
HP:0000602Ophthalmoplegia
HP:0001999Abnormal facial shape
HP:0002804Arthrogryposis multiplex congenita
HP:0100543Cognitive impairment

Эпидемиология (2)

Point prevalence
<1 / 1 000 000
Worldwide
Cases/families
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы