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Benign Samaritan congenital myopathy

ORPHA:324581DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

RYR1
ryanodine receptor 1
Disease-causing germline mutation(s) in
OMIM: 180901

Фенотипы (19)

Очень частый (80–99%)5
HP:0000286Epicanthus
HP:0000316Hypertelorism
HP:0000341Narrow forehead
HP:0001265Hyporeflexia
HP:0001290Generalized hypotonia
Частый (30–79%)3
HP:0001072Thickened skin
HP:0001270Motor delay
HP:0001612Weak cry
Периодический (5–29%)11
HP:0000160Narrow mouth
HP:0000268Dolichocephaly
HP:0000431Wide nasal bridge
HP:0001254Lethargy
HP:0002058Myopathic facies
HP:0002380Fasciculations
HP:0002795Abnormal respiratory system physiology
HP:0003687Centrally nucleated skeletal muscle fibers
HP:0011220Prominent forehead
HP:0031139Frog-leg posture
HP:0031237Internally nucleated skeletal muscle fibers

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы