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Autosomal non-syndromic agammaglobulinemia

ORPHA:33110Clinical subtypeAutosomal dominant, Autosomal recessiveAll ages

Ассоциированные гены (10)

SPI1
Spi-1 proto-oncogene
Disease-causing germline mutation(s) in
OMIM: 165170
PIK3CD
phosphatidylinositol-4,5-bisphosphate 3-kinase catalytic subunit delta
Disease-causing germline mutation(s) in
OMIM: 602839
IGHM
immunoglobulin heavy constant mu
Disease-causing germline mutation(s) in
OMIM: 147020
IGLL1
immunoglobulin lambda like polypeptide 1
Disease-causing germline mutation(s) in
OMIM: 146770
LRRC8A
leucine rich repeat containing 8 VRAC subunit A
Disease-causing germline mutation(s) in
OMIM: 608360
TCF3
transcription factor 3
Disease-causing germline mutation(s) in
OMIM: 147141
CD79A
CD79a molecule
Disease-causing germline mutation(s) in
OMIM: 112205
CD79B
CD79b molecule
Disease-causing germline mutation(s) in
OMIM: 147245
BLNK
B cell linker
Disease-causing germline mutation(s) in
OMIM: 604515
PIK3R1
phosphoinositide-3-kinase regulatory subunit 1
Disease-causing germline mutation(s) in
OMIM: 171833

Фенотипы (29)

Очень частый (80–99%)13
HP:0000246Sinusitis
HP:0000389Chronic otitis media
HP:0000509Conjunctivitis
HP:0000988Skin rash
HP:0001581Recurrent skin infections
HP:0001945Fever
HP:0002014Diarrhea
HP:0002205Recurrent respiratory infections
HP:0002719Recurrent infections
HP:0002721Immunodeficiency
HP:0004432Agammaglobulinemia
HP:0012378Fatigue
HP:0012735Cough
Частый (30–79%)3
HP:0001369Arthritis
HP:0001508Failure to thrive
HP:0002754Osteomyelitis
Периодический (5–29%)13
HP:0000218High palate
HP:0000286Epicanthus
HP:0000316Hypertelorism
HP:0001287Meningitis
HP:0001875Decreased total neutrophil count
HP:0001944Dehydration
HP:0002024Malabsorption
HP:0002110Bronchiectasis
HP:0012115Hepatitis
HP:0100658Cellulitis
HP:0100806Sepsis
HP:0200043Verrucae
HP:0000377Abnormal pinna morphology

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Europe

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы