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Fructose-1,6-bisphosphatase deficiency

ORPHA:348DiseaseAutosomal recessiveAll ages

Ассоциированные гены (1)

FBP1
fructose-bisphosphatase 1
Disease-causing germline mutation(s) in
OMIM: 611570

Фенотипы (34)

Очень частый (80–99%)4
HP:0001942Metabolic acidosis
HP:0001943Hypoglycemia
HP:0003128Lactic acidosis
HP:0012379Abnormal enzyme/coenzyme activity
Частый (30–79%)5
HP:0002013Vomiting
HP:0002014Diarrhea
HP:0002149Hyperuricemia
HP:0003162Fasting hypoglycemia
HP:0004913Intermittent lactic acidemia
Периодический (5–29%)24
HP:0000737Irritability
HP:0000980Pallor
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001252Hypotonia
HP:0001259Coma
HP:0001262Excessive daytime somnolence
HP:0001397Hepatic steatosis
HP:0001649Tachycardia
HP:0001946Ketosis
HP:0001998Neonatal hypoglycemia
HP:0002094Dyspnea
HP:0002098Respiratory distress
HP:0002119Ventriculomegaly
HP:0002240Hepatomegaly
HP:0002329Drowsiness
HP:0002876Episodic tachypnea
HP:0002910Elevated circulating hepatic transaminase concentration
HP:0003265Neonatal hyperbilirubinemia
HP:0004372Reduced consciousness/confusion
HP:0004879Intermittent hyperventilation
HP:0005949Apneic episodes in infancy
HP:0006582Reye syndrome-like episodes
HP:0040301Increased urinary glycerol
Очень редкий (1–4%)1
HP:0003348Hyperalaninemia

Эпидемиология (2)

Prevalence at birth
1-9 / 1 000 000
Italy
Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы