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Fucosidosis

ORPHA:349DiseaseAutosomal recessiveChildhood, Infancy

Ассоциированные гены (1)

FUCA1
alpha-L-fucosidase 1
Disease-causing germline mutation(s) in
OMIM: 612280

Фенотипы (31)

Очень частый (80–99%)17
HP:0000248Brachycephaly
HP:0000280Coarse facial features
HP:0000365Hearing impairment
HP:0000821Hypothyroidism
HP:0000943Dysostosis multiplex
HP:0000975Hyperhidrosis
HP:0001263Global developmental delay
HP:0001508Failure to thrive
HP:0001999Abnormal facial shape
HP:0002240Hepatomegaly
HP:0002808Kyphosis
HP:0005595Generalized hyperkeratosis
HP:0008155Mucopolysacchariduria
HP:0008430Anterior beaking of lumbar vertebrae
HP:0010864Intellectual disability, severe
HP:0011220Prominent forehead
HP:0100578Lipoatrophy
Частый (30–79%)9
HP:0001250Seizure
HP:0001252Hypotonia
HP:0001257Spasticity
HP:0001626Abnormality of the cardiovascular system
HP:0002510Spastic tetraplegia
HP:0003199Decreased muscle mass
HP:0005264Abnormality of the gallbladder
HP:0007957Corneal opacity
HP:0011276Vascular skin abnormality
Периодический (5–29%)5
HP:0000164Abnormality of the dentition
HP:0001063Acrocyanosis
HP:0001597Abnormality of the nail
HP:0001640Cardiomegaly
HP:0007256Abnormal pyramidal sign

Эпидемиология (4)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide
Prevalence at birth
1-9 / 1 000 000
Sweden
Prevalence at birth
1-9 / 1 000 000
Cuba

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы