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Progressive myoclonic epilepsy with dystonia

ORPHA:352596DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

TBC1D24
TBC1 domain family member 24
Disease-causing germline mutation(s) (loss of function) in
OMIM: 613577

Фенотипы (22)

Очень частый (80–99%)4
HP:0001332Dystonia
HP:0001336Myoclonus
HP:0002788Recurrent upper respiratory tract infections
HP:0007256Abnormal pyramidal sign
Частый (30–79%)9
HP:0000252Microcephaly
HP:0001326EEG with irregular generalized spike and wave complexes
HP:0002123Generalized myoclonic seizure
HP:0002133Status epilepticus
HP:0002188Delayed CNS myelination
HP:0002376Developmental regression
HP:0008935Generalized neonatal hypotonia
HP:0011968Feeding difficulties
HP:0200134Epileptic encephalopathy
Периодический (5–29%)8
HP:0001262Excessive daytime somnolence
HP:0001263Global developmental delay
HP:0001269Hemiparesis
HP:0002071Abnormality of extrapyramidal motor function
HP:0002301Hemiplegia
HP:0002506Diffuse cerebral atrophy
HP:0025152Poor visual behavior for age
HP:0100275Diffuse cerebellar atrophy
Очень редкий (1–4%)1
HP:0000648Optic atrophy

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы