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X-linked Charcot-Marie-Tooth disease type 6

ORPHA:352675DiseaseX-linked dominantChildhood

Ассоциированные гены (1)

PDK3
pyruvate dehydrogenase kinase 3
Disease-causing germline mutation(s) (gain of function) in
OMIM: 300906

Фенотипы (16)

Очень частый (80–99%)10
HP:0000762Decreased nerve conduction velocity
HP:0001288Gait disturbance
HP:0001761Pes cavus
HP:0002378Hand tremor
HP:0002936Distal sensory impairment
HP:0003438Absent Achilles reflex
HP:0003482EMG: axonal abnormality
HP:0007141Sensorimotor neuropathy
HP:0007340Lower limb muscle weakness
HP:0008944Distal lower limb amyotrophy
Частый (30–79%)4
HP:0002166Impaired vibration sensation in the lower limbs
HP:0003236Elevated circulating creatine kinase concentration
HP:0003376Steppage gait
HP:0003393Thenar muscle atrophy
Периодический (5–29%)2
HP:0000407Sensorineural hearing impairment
HP:0001270Motor delay

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы