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Familial glucocorticoid deficiency

ORPHA:361DiseaseAutosomal recessiveChildhood, Infancy

Ассоциированные гены (5)

STAR
steroidogenic acute regulatory protein
Candidate gene tested in
OMIM: 600617
MC2R
melanocortin 2 receptor
Disease-causing germline mutation(s) in
OMIM: 607397
MRAP
melanocortin 2 receptor accessory protein
Disease-causing germline mutation(s) in
OMIM: 609196
TXNRD2
thioredoxin reductase 2
Disease-causing germline mutation(s) (loss of function) in
OMIM: 606448
NNT
nicotinamide nucleotide transhydrogenase
Disease-causing germline mutation(s) in
OMIM: 607878

Фенотипы (36)

Облигатный (100%)2
HP:0000846Adrenal insufficiency
HP:0008163Decreased circulating cortisol level
Очень частый (80–99%)7
HP:0001508Failure to thrive
HP:0002615Hypotension
HP:0007440Generalized hyperpigmentation
HP:0011043Abnormality of circulating adrenocorticotropin level
HP:0012734Ketotic hypoglycemia
HP:0031076Impaired cortisol response to insulin stimulation test
HP:0031214Decreased circulating dehydroepiandrosterone level
Частый (30–79%)13
HP:0000127Renal salt wasting
HP:0001824Weight loss
HP:0002013Vomiting
HP:0002014Diarrhea
HP:0002019Constipation
HP:0002039Anorexia
HP:0002153Hyperkalemia
HP:0002173Hypoglycemic seizures
HP:0002574Episodic abdominal pain
HP:0002719Recurrent infections
HP:0002902Hyponatremia
HP:0012432Chronic fatigue
HP:0012605Hypernatriuria
Периодический (5–29%)5
HP:0000826Precocious puberty
HP:0004319Decreased circulating aldosterone level
HP:0025451Testicular adrenal rest tumor
HP:0000028Cryptorchidism
HP:0000098Tall stature
Очень редкий (1–4%)8
HP:0000010Recurrent urinary tract infections
HP:0000027Azoospermia
HP:0000851Congenital hypothyroidism
HP:0001249Intellectual disability
HP:0001325Hypoglycemic coma
HP:0001639Hypertrophic cardiomyopathy
HP:0002445Tetraplegia
HP:0100618Leydig cell neoplasia
Исключён (0%)1
HP:0002960Autoimmunity

Эпидемиология (2)

Point prevalence
1-9 / 1 000 000
Ireland
Point prevalence
Unknown
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы