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Glycogen storage disease due to liver glycogen phosphorylase deficiency

ORPHA:369DiseaseAutosomal recessiveChildhood

Ассоциированные гены (1)

PYGL
glycogen phosphorylase L
Disease-causing germline mutation(s) in
OMIM: 613741

Фенотипы (28)

Очень частый (80–99%)2
HP:0002240Hepatomegaly
HP:0006568Increased hepatic glycogen content
Частый (30–79%)8
HP:0000938Osteopenia
HP:0000939Osteoporosis
HP:0001508Failure to thrive
HP:0000823Delayed puberty
HP:0001510Growth delay
HP:0001943Hypoglycemia
HP:0001946Ketosis
HP:0002910Elevated circulating hepatic transaminase concentration
Периодический (5–29%)12
HP:0000737Irritability
HP:0001252Hypotonia
HP:0001270Motor delay
HP:0001395Hepatic fibrosis
HP:0002360Sleep abnormality
HP:0003077Hyperlipidemia
HP:0003270Abdominal distention
HP:0003710Exercise-induced muscle cramps
HP:0004322Short stature
HP:0004913Intermittent lactic acidemia
HP:0006580Portal fibrosis
HP:0030973Postexertional malaise
Очень редкий (1–4%)6
HP:0000077Abnormality of the kidney
HP:0000093Proteinuria
HP:0001394Cirrhosis
HP:0001402Hepatocellular carcinoma
HP:0001639Hypertrophic cardiomyopathy
HP:0011997Postprandial hyperlactemia

Эпидемиология (3)

Point prevalence
Unknown
Worldwide
Prevalence at birth
1-9 / 100 000
Israel
Prevalence at birth
1-9 / 100 000
Specific population

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы