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Intellectual disability-eye abnormalities-microcephaly-peripheral spasticity syndrome

ORPHA:404473Malformation syndromeUnknownInfancy

Ассоциированные гены (1)

CTNNB1
catenin beta 1
Disease-causing germline mutation(s) in
OMIM: 116806

Фенотипы (32)

Очень частый (80–99%)7
HP:0000252Microcephaly
HP:0001249Intellectual disability
HP:0001257Spasticity
HP:0001270Motor delay
HP:0001999Abnormal facial shape
HP:0002465Poor speech
HP:0008936Axial hypotonia
Частый (30–79%)4
HP:0000478Abnormality of the eye
HP:0000708Atypical behavior
HP:0002376Developmental regression
HP:0011451Congenital microcephaly
Периодический (5–29%)19
HP:0000219Thin upper lip vermilion
HP:0000319Smooth philtrum
HP:0000343Long philtrum
HP:0000430Underdeveloped nasal alae
HP:0000455Broad nasal tip
HP:0000486Strabismus
HP:0000540Hypermetropia
HP:0000545Myopia
HP:0000718Aggressive behavior
HP:0000729Autistic behavior
HP:0002079Hypoplasia of the corpus callosum
HP:0002119Ventriculomegaly
HP:0002144Tethered cord
HP:0002188Delayed CNS myelination
HP:0002360Sleep abnormality
HP:0003396Syringomyelia
HP:0009765Low hanging columella
HP:0025160Abnormal temper tantrums
HP:0100716Self-injurious behavior
Очень редкий (1–4%)2
HP:0000365Hearing impairment
HP:0001250Seizure

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы