← Назад

Pontocerebellar hypoplasia type 10

ORPHA:411493Malformation syndromeAutosomal recessiveNeonatal

Ассоциированные гены (1)

CLP1
cleavage factor polyribonucleotide kinase subunit 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 608757

Фенотипы (27)

Очень частый (80–99%)4
HP:0000750Delayed speech and language development
HP:0001347Hyperreflexia
HP:0002194Delayed gross motor development
HP:0010862Delayed fine motor development
Частый (30–79%)16
HP:0000430Underdeveloped nasal alae
HP:0000431Wide nasal bridge
HP:0000520Proptosis
HP:0000527Long eyelashes
HP:0000637Long palpebral fissure
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001257Spasticity
HP:0001263Global developmental delay
HP:0001276Hypertonia
HP:0001290Generalized hypotonia
HP:0001510Growth delay
HP:0002421Poor head control
HP:0002538Abnormality of the cerebral cortex
HP:0002553Highly arched eyebrow
HP:0007141Sensorimotor neuropathy
Периодический (5–29%)4
HP:0000737Irritability
HP:0002363Abnormal brainstem morphology
HP:0009879Simplified gyral pattern
HP:0025405Visual fixation instability
Очень редкий (1–4%)3
HP:0000486Strabismus
HP:0000505Visual impairment
HP:0000648Optic atrophy

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы