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Isolated sedoheptulokinase deficiency

ORPHA:440713DiseaseAutosomal recessiveAntenatal, Neonatal

Ассоциированные гены (1)

SHPK
sedoheptulokinase
Disease-causing germline mutation(s) in
OMIM: 605060

Фенотипы (28)

Облигатный (100%)3
HP:0001371Flexion contracture
HP:0002804Arthrogryposis multiplex congenita
HP:0012768Neonatal asphyxia
Частый (30–79%)25
HP:0000023Inguinal hernia
HP:0000083Renal insufficiency
HP:0000091Abnormal renal tubule morphology
HP:0000239Large fontanelles
HP:0000256Macrocephaly
HP:0000348High forehead
HP:0000586Shallow orbits
HP:0000601Hypotelorism
HP:0001385Hip dysplasia
HP:0001396Cholestasis
HP:0001409Portal hypertension
HP:0001540Diastasis recti
HP:0001623Breech presentation
HP:0001903Anemia
HP:0002119Ventriculomegaly
HP:0002570Steatorrhea
HP:0002611Cholestatic liver disease
HP:0004322Short stature
HP:0004840Hypochromic microcytic anemia
HP:0008850Severe postnatal growth retardation
HP:0011400Abnormal CNS myelination
HP:0011998Postprandial hyperglycemia
HP:0012115Hepatitis
HP:0012157Subcortical cerebral atrophy
HP:0100886Abnormality of globe location

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы