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Autosomal dominant mitochondrial myopathy with exercise intolerance

ORPHA:457050DiseaseAutosomal dominantChildhood, Infancy

Ассоциированные гены (1)

CHCHD10
coiled-coil-helix-coiled-coil-helix domain containing 10
Disease-causing germline mutation(s) in
OMIM: 615903

Фенотипы (13)

Частый (30–79%)12
HP:0002091Restrictive ventilatory defect
HP:0002151Increased circulating lactate concentration
HP:0003200Ragged-red muscle fibers
HP:0003546Exercise intolerance
HP:0003722Neck flexor weakness
HP:0004322Short stature
HP:0008180Mildly elevated creatine kinase
HP:0008994Proximal muscle weakness in lower limbs
HP:0009053Distal lower limb muscle weakness
HP:0012240Increased intramyocellular lipid droplets
HP:0030319Weakness of facial musculature
HP:0040014Increased mitochondrial number
Периодический (5–29%)1
HP:0008997Proximal muscle weakness in upper limbs

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы