← Назад

Acute infantile liver failure-cerebellar ataxia-peripheral sensory motor neuropathy syndrome

ORPHA:466794DiseaseAutosomal recessiveInfancy

Ассоциированные гены (1)

SCYL1
SCY1 like pseudokinase 1
Disease-causing germline mutation(s) in
OMIM: 607982

Фенотипы (25)

Частый (30–79%)20
HP:0000641Dysmetric saccades
HP:0001152Saccadic smooth pursuit
HP:0001256Intellectual disability, mild
HP:0001263Global developmental delay
HP:0001265Hyporeflexia
HP:0001395Hepatic fibrosis
HP:0001433Hepatosplenomegaly
HP:0001945Fever
HP:0002066Gait ataxia
HP:0002073Progressive cerebellar ataxia
HP:0002080Intention tremor
HP:0002359Frequent falls
HP:0003401Paresthesia
HP:0003474Somatic sensory dysfunction
HP:0006554Acute hepatic failure
HP:0006855Cerebellar vermis atrophy
HP:0009053Distal lower limb muscle weakness
HP:0009055Generalized limb muscle atrophy
HP:0009830Peripheral neuropathy
HP:0025268Stuttering
Очень редкий (1–4%)4
HP:0000648Optic atrophy
HP:0001257Spasticity
HP:0001347Hyperreflexia
HP:0001762Talipes equinovarus
Исключён (0%)1
HP:0007663Reduced visual acuity

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы