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Tubulinopathy-associated dysgyria

ORPHA:467166DiseaseAutosomal dominant, Not applicableInfancy

Ассоциированные гены (3)

TUBA1A
tubulin alpha 1a
Disease-causing germline mutation(s) in
OMIM: 602529
TUBB2B
tubulin beta 2B class IIb
Disease-causing germline mutation(s) in
OMIM: 612850
TUBB3
tubulin beta 3 class III
Disease-causing germline mutation(s) in
OMIM: 602661

Фенотипы (24)

Очень частый (80–99%)9
HP:0000252Microcephaly
HP:0001263Global developmental delay
HP:0001273Abnormal corpus callosum morphology
HP:0001320Cerebellar vermis hypoplasia
HP:0002363Abnormal brainstem morphology
HP:0010663Abnormality of thalamus morphology
HP:0012110Hypoplasia of the pons
HP:0012502Abnormality of the internal capsule
HP:0032398Dysgyria
Частый (30–79%)8
HP:0000486Strabismus
HP:0000657Oculomotor apraxia
HP:0001302Pachygyria
HP:0002119Ventriculomegaly
HP:0007018Attention deficit hyperactivity disorder
HP:0012547Abnormal involuntary eye movements
HP:0031882Agyria
HP:0040327Abnormal morphology of the olfactory bulb
Периодический (5–29%)7
HP:0000256Macrocephaly
HP:0001251Ataxia
HP:0001252Hypotonia
HP:0001488Bilateral ptosis
HP:0002121Generalized non-motor (absence) seizure
HP:0012469Infantile spasms
HP:0020214Startle-induced seizure

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы