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Aceruloplasminemia

ORPHA:48818DiseaseAutosomal recessiveAdult, Elderly

Ассоциированные гены (1)

CP
ceruloplasmin
Disease-causing germline mutation(s) (loss of function) in
OMIM: 117700

Фенотипы (41)

Очень частый (80–99%)6
HP:0000707Abnormality of the nervous system
HP:0003281Increased circulating ferritin concentration
HP:0004840Hypochromic microcytic anemia
HP:0005505Refractory anemia
HP:0012379Abnormal enzyme/coenzyme activity
HP:0025498Aceruloplasminemia
Частый (30–79%)16
HP:0000546Retinal degeneration
HP:0000608Macular degeneration
HP:0000819Diabetes mellitus
HP:0001251Ataxia
HP:0001260Dysarthria
HP:0001332Dystonia
HP:0002066Gait ataxia
HP:0002070Limb ataxia
HP:0002072Chorea
HP:0004305Involuntary movements
HP:0007703Abnormality of retinal pigmentation
HP:0010837Decreased circulating ceruloplasmin concentration
HP:0011967Decreased circulating copper concentration
HP:0012465Elevated hepatic iron concentration
HP:0040303Decreased serum iron
HP:0100543Cognitive impairment
Периодический (5–29%)17
HP:0000273Facial grimacing
HP:0000473Torticollis
HP:0000639Nystagmus
HP:0000643Blepharospasm
HP:0000741Apathy
HP:0001300Parkinsonism
HP:0001337Tremor
HP:0001635Congestive heart failure
HP:0002063Rigidity
HP:0002304Akinesia
HP:0002354Memory impairment
HP:0010994Abnormal corpus striatum morphology
HP:0012090Abnormal pancreas morphology
HP:0012179Craniofacial dystonia
HP:0012675Iron accumulation in brain
HP:0012696Abnormal thalamic MRI signal intensity
HP:0100321Abnormality of the dentate nucleus
Исключён (0%)2
HP:0001394Cirrhosis
HP:0001395Hepatic fibrosis

Эпидемиология (2)

Point prevalence
1-9 / 1 000 000
Japan
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы