← Назад

Severe growth deficiency-strabismus-extensive dermal melanocytosis-intellectual disability syndrome

ORPHA:488627Malformation syndromeAutosomal recessiveInfancy

Ассоциированные гены (1)

PUS3
pseudouridine synthase 3
Disease-causing germline mutation(s) in
OMIM: 616283

Фенотипы (40)

Очень частый (80–99%)4
HP:0000280Coarse facial features
HP:0001250Seizure
HP:0001263Global developmental delay
HP:0001531Failure to thrive in infancy
Частый (30–79%)10
HP:0000093Proteinuria
HP:0000253Progressive microcephaly
HP:0001288Gait disturbance
HP:0002120Cerebral cortical atrophy
HP:0002187Intellectual disability, profound
HP:0002465Poor speech
HP:0007052Multifocal cerebral white matter abnormalities
HP:0007334Bilateral tonic-clonic seizure with focal onset
HP:0012213Decreased glomerular filtration rate
HP:0012622Chronic kidney disease
Периодический (5–29%)26
HP:0000100Nephrotic syndrome
HP:0000407Sensorineural hearing impairment
HP:0000486Strabismus
HP:0000505Visual impairment
HP:0000592Blue sclerae
HP:0000639Nystagmus
HP:0000709Psychosis
HP:0000718Aggressive behavior
HP:0000961Cyanosis
HP:0001260Dysarthria
HP:0001290Generalized hypotonia
HP:0001344Absent speech
HP:0001347Hyperreflexia
HP:0001970Tubulointerstitial nephritis
HP:0002015Dysphagia
HP:0002079Hypoplasia of the corpus callosum
HP:0002119Ventriculomegaly
HP:0002141Gait imbalance
HP:0002193Pseudobulbar behavioral symptoms
HP:0002367Visual hallucinations
HP:0002857Genu valgum
HP:0006956Dilation of lateral ventricles
HP:0006989Dysplastic corpus callosum
HP:0040329Multifocal hyperintensity of cerebral white matter on MRI
HP:0100702Arachnoid cyst
HP:0100814Blue nevus

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы