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Autosomal recessive complex spastic paraplegia due to Kennedy pathway dysfunction

ORPHA:506353DiseaseAutosomal recessiveChildhood, Infancy

Ассоциированные гены (1)

SELENOI
selenoprotein I
Disease-causing germline mutation(s) (loss of function) in
OMIM: 607915

Фенотипы (22)

Облигатный (100%)10
HP:0007020Progressive spastic paraplegia
HP:0000252Microcephaly
HP:0008848Moderately short stature
HP:0008376Nasal, dysarthic speech
HP:0002194Delayed gross motor development
HP:0002191Progressive spasticity
HP:0002395Lower limb hyperreflexia
HP:0011448Ankle clonus
HP:0007814Retinal pigment epithelial mottling
HP:0007199Progressive spastic paraparesis
Частый (30–79%)9
HP:0001256Intellectual disability, mild
HP:0003487Babinski sign
HP:0000175Cleft palate
HP:0000193Bifid uvula
HP:0030625Hyporeflective spaces on macular OCT
HP:0007220Demyelinating motor neuropathy
HP:0001250Seizure
HP:0007768Central retinal vessel vascular tortuosity
HP:0007663Reduced visual acuity
Периодический (5–29%)3
HP:0004302Functional motor deficit
HP:0030182Tetraplegia/tetraparesis
HP:0002493Upper motor neuron dysfunction

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы