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Ethylmalonic encephalopathy

ORPHA:51188DiseaseAutosomal recessiveInfancy, Neonatal

Ассоциированные гены (1)

ETHE1
ETHE1 persulfide dioxygenase
Disease-causing germline mutation(s) in
OMIM: 608451

Фенотипы (18)

Очень частый (80–99%)2
HP:0001298Encephalopathy
HP:0003219Ethylmalonic aciduria
Частый (30–79%)15
HP:0000967Petechiae
HP:0001063Acrocyanosis
HP:0001249Intellectual disability
HP:0001250Seizure
HP:0001251Ataxia
HP:0001290Generalized hypotonia
HP:0001508Failure to thrive
HP:0002014Diarrhea
HP:0002071Abnormality of extrapyramidal motor function
HP:0002376Developmental regression
HP:0003128Lactic acidosis
HP:0007256Abnormal pyramidal sign
HP:0012751Abnormal basal ganglia MRI signal intensity
HP:0012758Neurodevelopmental delay
HP:0012841Retinal vascular tortuosity
Периодический (5–29%)1
HP:0012747Abnormal brainstem MRI signal intensity

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы