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Corpus callosum agenesis-intellectual disability-coloboma-micrognathia syndrome

ORPHA:52055Malformation syndromeX-linked recessiveInfancy, Neonatal

Ассоциированные гены (1)

IGBP1
immunoglobulin binding protein 1
Disease-causing germline mutation(s) in
OMIM: 300139

Фенотипы (24)

Очень частый (80–99%)16
HP:0000256Macrocephaly
HP:0000278Retrognathia
HP:0000348High forehead
HP:0000365Hearing impairment
HP:0000369Low-set ears
HP:0000377Abnormal pinna morphology
HP:0000378Cupped ear
HP:0000407Sensorineural hearing impairment
HP:0000470Short neck
HP:0000494Downslanted palpebral fissures
HP:0000639Nystagmus
HP:0000767Pectus excavatum
HP:0001249Intellectual disability
HP:0001274Agenesis of corpus callosum
HP:0002650Scoliosis
HP:0004322Short stature
Частый (30–79%)8
HP:0000175Cleft palate
HP:0000218High palate
HP:0000426Prominent nasal bridge
HP:0000453Choanal atresia
HP:0000588Optic disc coloboma
HP:0000612Iris coloboma
HP:0001629Ventricular septal defect
HP:0001643Patent ductus arteriosus

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы