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X-linked lymphoproliferative disease due to XIAP deficiency

ORPHA:538934DiseaseX-linked recessiveAdolescent, Adult, Childhood, Infancy

Ассоциированные гены (1)

XIAP
X-linked inhibitor of apoptosis
Disease-causing germline mutation(s) in
OMIM: 300079

Фенотипы (22)

Очень частый (80–99%)1
HP:0002721Immunodeficiency
Частый (30–79%)7
HP:0001744Splenomegaly
HP:0001876Pancytopenia
HP:0001954Recurrent fever
HP:0005229Jejunoileal ulceration
HP:0012115Hepatitis
HP:0034799Splenic hemophagocytosis
HP:0100280Crohn's disease
Периодический (5–29%)13
HP:0000083Renal insufficiency
HP:0000123Nephritis
HP:0000554Uveitis
HP:0001369Arthritis
HP:0002037Inflammation of the large intestine
HP:0002583Colitis
HP:0002719Recurrent infections
HP:0004313Decreased circulating antibody level
HP:0012219Erythema nodosum
HP:0030151Cholangitis
HP:0031292Cutaneous abscess
HP:0031693Severe Epstein Barr virus infection
HP:0040218Reduced natural killer cell count
Очень редкий (1–4%)1
HP:0001399Hepatic failure

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы