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MODY

ORPHA:552DiseaseAutosomal dominant, Not applicableAdolescent, Adult, Childhood

Ассоциированные гены (13)

ABCC8
ATP binding cassette subfamily C member 8
Disease-causing germline mutation(s) in
OMIM: 600509
CEL
carboxyl ester lipase
Disease-causing germline mutation(s) in
OMIM: 114840
GCK
glucokinase
Disease-causing germline mutation(s) in
OMIM: 138079
HNF4A
hepatocyte nuclear factor 4 alpha
Disease-causing germline mutation(s) in
OMIM: 600281
KCNJ11
potassium inwardly rectifying channel subfamily J member 11
Disease-causing germline mutation(s) in
OMIM: 600937
KLF11
KLF transcription factor 11
Disease-causing germline mutation(s) in
OMIM: 603301
NEUROD1
neuronal differentiation 1
Disease-causing germline mutation(s) in
OMIM: 601724
PDX1
pancreatic and duodenal homeobox 1
Disease-causing germline mutation(s) in
OMIM: 600733
HNF1A
HNF1 homeobox A
Disease-causing germline mutation(s) in
OMIM: 142410
INS
insulin
Disease-causing germline mutation(s) in
OMIM: 176730
PAX4
paired box 4
Disease-causing germline mutation(s) in
OMIM: 167413
BLK
BLK proto-oncogene, Src family tyrosine kinase
Disease-causing germline mutation(s) in
OMIM: 191305
APPL1
adaptor protein, phosphotyrosine interacting with PH domain and leucine zipper 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 604299

Фенотипы (27)

Частый (30–79%)8
HP:0001952Glucose intolerance
HP:0003074Hyperglycemia
HP:0003076Glycosuria
HP:0004924Abnormal oral glucose tolerance
HP:0030794Abnormal C-peptide level
HP:0040214Abnormal circulating insulin concentration
HP:0040216Hypoinsulinemia
HP:0040217Elevated hemoglobin A1c
Периодический (5–29%)9
HP:0000112Nephropathy
HP:0000488Retinopathy
HP:0000825Hyperinsulinemic hypoglycemia
HP:0000831Insulin-resistant diabetes mellitus
HP:0001511Intrauterine growth retardation
HP:0001520Large for gestational age
HP:0001998Neonatal hypoglycemia
HP:0008255Transient neonatal diabetes mellitus
HP:0025502Overweight
Очень редкий (1–4%)7
HP:0000077Abnormality of the kidney
HP:0000107Renal cyst
HP:0000119Abnormality of the genitourinary system
HP:0001513Obesity
HP:0001738Exocrine pancreatic insufficiency
HP:0002594Pancreatic hypoplasia
HP:0012028Hepatocellular adenoma
Исключён (0%)3
HP:0000956Acanthosis nigricans
HP:0001953Diabetic ketoacidosis
HP:0030057Autoimmune antibody positivity

Эпидемиология (2)

Point prevalence
1-5 / 10 000
Europe
Point prevalence
1-5 / 10 000
United Kingdom

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы