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Pancreatic agenesis-holoprosencephaly syndrome

ORPHA:556955DiseaseAutosomal dominantAntenatal

Ассоциированные гены (1)

CNOT1
CCR4-NOT transcription complex subunit 1
Disease-causing germline mutation(s) in
OMIM: 604917

Фенотипы (23)

Частый (30–79%)11
HP:0000857Neonatal insulin-dependent diabetes mellitus
HP:0001274Agenesis of corpus callosum
HP:0001360Holoprosencephaly
HP:0001511Intrauterine growth retardation
HP:0001518Small for gestational age
HP:0011467Absent gallbladder
HP:0012443Abnormality of brain morphology
HP:0030795Reduced C-peptide level
HP:0031209Decreased lipoprotein lipase activity
HP:0100801Pancreatic aplasia
HP:0410289Hypoamylasemia
Периодический (5–29%)12
HP:0000218High palate
HP:0000269Prominent occiput
HP:0000340Sloping forehead
HP:0000369Low-set ears
HP:0000377Abnormal pinna morphology
HP:0000601Hypotelorism
HP:0002507Semilobar holoprosencephaly
HP:0006315Single median maxillary incisor
HP:0009658Aplasia/Hypoplasia of the phalanges of the thumb
HP:0010669Hypoplasia of the zygomatic bone
HP:0010938Abnormal external nose morphology
HP:0012418Hypoxemia

Эпидемиология (2)

Cases/families
Worldwide
Point prevalence
<1 / 1 000 000
Worldwide

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы