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Mucolipidosis type IV

ORPHA:578DiseaseAutosomal recessiveInfancy

Ассоциированные гены (1)

MCOLN1
mucolipin TRP cation channel 1
Disease-causing germline mutation(s) (loss of function) in
OMIM: 605248

Фенотипы (27)

Очень частый (80–99%)13
HP:0000486Strabismus
HP:0000488Retinopathy
HP:0000613Photophobia
HP:0000708Atypical behavior
HP:0001249Intellectual disability
HP:0001288Gait disturbance
HP:0001344Absent speech
HP:0001347Hyperreflexia
HP:0004345Abnormality of ganglioside metabolism
HP:0007281Developmental stagnation
HP:0007957Corneal opacity
HP:0010318Aplasia/Hypoplasia of the abdominal wall musculature
HP:0011020Abnormality of mucopolysaccharide metabolism
Частый (30–79%)4
HP:0000639Nystagmus
HP:0001251Ataxia
HP:0001252Hypotonia
HP:0002353EEG abnormality
Периодический (5–29%)10
HP:0000232Everted lower lip vermilion
HP:0000252Microcephaly
HP:0000280Coarse facial features
HP:0000512Abnormal electroretinogram
HP:0000691Microdontia
HP:0000982Palmoplantar keratoderma
HP:0002816Genu recurvatum
HP:0004422Biparietal narrowing
HP:0005105Abnormal nasal morphology
HP:0007703Abnormality of retinal pigmentation

Эпидемиология (3)

Point prevalence
Unknown
Worldwide
Prevalence at birth
1-9 / 1 000 000
Sweden
Prevalence at birth
1-9 / 100 000
Specific population

Лекарства и терапия

Источник: Open Targets Platform (в реальном времени)

Клинические исследования

Источник: ClinicalTrials.gov (в реальном времени)

Внешние ресурсы